Dysgenetic polycystic disease of the minor and submandibular salivary glands.

نویسندگان

  • Eleftherios Koudounarakis
  • Stefan Willems
  • Baris Karakullukcu
چکیده

BACKGROUND Dysgenetic polycystic salivary gland disease is a rare pathology. No case of minor salivary gland involvement has been reported in the literature. METHODS A female patient presented with bilateral tumors of the parotid glands, bilateral submandibular gland enlargement, and multiple cystic lesions of the oral mucosa. MRI of the neck was performed along with fine-needle aspiration (FNA) of the parotid tumors and excisional biopsy of an oral lesion. RESULTS Imaging and FNA findings of the parotid glands were suggestive of bilateral Warthin tumors. Excisional biopsy of the oral lesion revealed a minor salivary gland with histopathological features of dysgenetic polycystic salivary gland disease. Submandibular gland enlargement was also attributed to this rare entity based on the imaging characteristics. CONCLUSION This is the first report of dysgenetic polycystic salivary gland disease of the minor salivary glands, combined with involvement of the submandibular glands and bilateral Warthin tumors of the parotid gland. © 2016 Wiley Periodicals, Inc. Head Neck 38: E2437-E2439, 2016.

برای دانلود متن کامل این مقاله و بیش از 32 میلیون مقاله دیگر ابتدا ثبت نام کنید

ثبت نام

اگر عضو سایت هستید لطفا وارد حساب کاربری خود شوید

منابع مشابه

Dysgenetic Polycystic Disease of Minor Salivary Gland: A Rare Case Report and Review of the Literature

Polycystic (dysgenetic) disease of the salivary glands is a rare entity that has only recently been described in the literature. The disease is more commonly seen in females and majority of the cases have presented as bilateral parotid gland swellings. This case presenting in a 21-year-old male is the first of this unusual entity involving solely the minor salivary gland on the lower lip. This ...

متن کامل

Sclerosing Polycystic Adenosis of the minor salivary gland: case report.

Sclerosing Polycystic Adenosis (SPA) is a rare disease of the salivary glands, first described by Smith et al. in 1996, with histomorphological aspects similar to those from breast fibrocystic disorders1. Its pathogenesis is still unclear; however, it is considered a pseudo-neoplastic or reactive process. Recently, Skálová et al. showed clonality in six SPA cases. SPA affects mainly the parotid...

متن کامل

Sclerosing Polycystic Adenosis of the Nasal Septum: The Risk of Misdiagnosis

Sclerosing polycyctic adenosis (SPA) is a rare lesion of unknown etiology morphologically resembling fibrocystic changes of the breast. To date, approximately 41 cases of SPA have been reported. Most cases of SPA have originated in the parotid and submandibular glands, with a few cases of intra-oral minor salivary gland origin. This is the first reported case of sclerosing polycystic adenosis o...

متن کامل

Large Multiple Sialoliths of Bilateral Submandibular Glands: A Case Report

 Introduction: Sialolithiasis is a most common disease of salivary glands most commonly occurs in submandibular gland system. Simultaneous sialolithiasis in more than one salivary gland and multiple stone formations have been reported in only 5% and 3% of cases, respectively. In this article, a rare case of bilateral presence of various stones in different sizes and shapes in the submandibular ...

متن کامل

ذخیره در منابع من


  با ذخیره ی این منبع در منابع من، دسترسی به آن را برای استفاده های بعدی آسان تر کنید

برای دانلود متن کامل این مقاله و بیش از 32 میلیون مقاله دیگر ابتدا ثبت نام کنید

ثبت نام

اگر عضو سایت هستید لطفا وارد حساب کاربری خود شوید

عنوان ژورنال:
  • Head & neck

دوره 38 6  شماره 

صفحات  -

تاریخ انتشار 2016